Glycogen Response to Enzyme Replacement Therapy in Pompe Disease

2023-508000-37-01 Therapeutic use (Phase IV) Ongoing, recruiting

Start 13 Feb 2024 · Status Ongoing, recruiting · 1 EU/EEA countries · 1 sites

Overview

Sponsor-declared trial summary

Phase Therapeutic use (Phase IV)
Status Ongoing, recruiting
Participants planned 10
Countries 1
Sites 1

Pompe Disease

The objective of this trial it to characterize how muscle glycogen is affected by enzyme replacement therapy in treatment naïve patients with Pompe Disease.

Key facts

Sponsor
Rigshospitalet
Participant type
Patients
Age range
18-64 years, 65+ years
Gender
Male and Female
Therapeutic area
Diseases [C] - Nutritional and Metabolic Diseases [C18], Diseases [C] - Musculoskeletal Diseases [C05], Diseases [C] - Congenital, Hereditary, and Neonatal Diseases and Abnormalities [C16]
Trial duration
13 Feb 2024 → ongoing
Decision date (initial)
2024-01-16
Transition trial
No
Low-intervention
No
Rare-disease indication
Yes
Vulnerable population
No
Funding sources
Sanofi

Trial design

CTIS Part I — objectives, methods, condition coding

Main objective

Scope: Pharmacodynamic

The objective of this trial it to characterize how muscle glycogen is affected by enzyme replacement therapy in treatment naïve patients with Pompe Disease.

Conditions and MedDRA coding

Pompe Disease

VersionLevelCodeTermSystem organ class
20.0 LLT 10075703 Pompe's disease adult onset 10010331

Regulatory references

Plan to share IPD
Yes
IPD plan description
Study only evaluates 3 individuals. Individual data will be published in peer reviewed journal.
EU CT numberTitleSponsor
2023-508000-37-00 GLYCOGEN RESPONSE TO ENZYME REPLACEMENT THERAPY IN POMPE DISEASE Rigshospitalet

Eligibility criteria

Principal inclusion / exclusion criteria as submitted by sponsor

Inclusion criteria 3

  1. Subjects with genetically verified Late-onset Pompe Disease
  2. Age ≥18
  3. Naïve to enzyme replacement therapy

Exclusion criteria 7

  1. Ferrous objects in or around the body
  2. Pacemaker or other implanted electronic devices
  3. Claustrophobia
  4. Inability to understand the purpose of the trial or corporate for the conduction of the experiments
  5. Participation in other trials that may interfere with the results
  6. Competing conditions at risk of compromising the results of the study, evaluated by the investigator
  7. Pregnancy

Endpoints

Primary and secondary outcome measures (English text)

Primary endpoints 1

  1. Change in glycogen concentration of the hamstring muscles between baseline and 12-month follow-up

Secondary endpoints 5

  1. Change in glycogen concentration of the calf, hamstring, anterior thigh, and lumbar muscles over time – both within the first treatment cycle, and at 3, 6 and 12-months follow-up
  2. Change in fat-fraction of the calf, hamstring, anterior thigh, and lumbar muscles from baseline to 3, 6 and 12-months follow-up.
  3. Correlations between baseline glycogen levels and change in FVC between baseline and 12-months follow-up.
  4. Correlations between baseline glycogen levels and change in 6MWT between baseline and 12-months follow-up.
  5. Correlations between baseline glycogen levels and change in fat-fraction of the calf, hamstring, anterior thigh, and lumbar muscles from baseline to 12-months follow-up.

Investigational products

Investigational medicinal products (IMPs), comparators, placebo, auxiliary

Test 1

Nexviadyme 100 mg powder for concentrate for solution for infusion

PRD9787959 · Product

Active substance
Avalglucosidase Alfa
Pharmaceutical form
SOLUTION FOR INFUSION
Route of administration
INFUSION
Max daily dose
1.5 mg/Kg milligram(s)/kilogram
Max total dose
520 mg/Kg milligram(s)/kilogram
Max treatment duration
12 Month(s)
Authorisation status
Authorised
ATC code
NOTASSIGN — -
Marketing authorisation
EU/1/21/1579/001
MA holder
SANOFI B.V.
MA country
Liechtenstein
Paediatric formulation
No
Orphan designation
No
Modified vs. Marketing Authorisation
No

Sponsors and contacts

Sponsor organisations, regulatory contacts, third parties

Rigshospitalet

Sponsor organisation
Rigshospitalet
Address
Blegdamsvej 9
City
Copenhagen Oe
Postcode
2100
Country
Denmark

Scientific contact point

Organisation
Rigshospitalet
Contact name
Mads Stemmerik

Public contact point

Organisation
Rigshospitalet
Contact name
Mads Stemmerik

Third parties 1

OrganisationCity, countryDuties
Frederiksberg Hospital
ORG-100028217
Frederiksberg, Denmark On site monitoring

Locations

1 EU/EEA country · 1 investigational sites

By country

CountryMS statusPlanned subjectsSites
Denmark Ongoing, recruiting 10 1
Rest of world 0

Investigational sites

Denmark

1 site · Ongoing, recruiting
Rigshospitalet
Copenhagen Neuromuscular Center, Blegdamsvej 9, 2100, Copenhagen Oe

Country notifications

Trial-start, recruitment-start, end and early-termination notifications submitted per Member State

Country Trial startTrial end Recruitment startRecruitment end Early termination
Denmark 2024-02-13 2024-02-13

Results and documents

Annex IV summary of results, Annex V layperson summary, and all documents registered in CTIS for this trial

Documents 8 files

Public protocol annexes, IB summaries, regulatory submissions and post-authorisation documents registered in CTIS.

TypeTitleVersion
Protocol (for publication) Protokol 7T Pompe 2
Protocol (for publication) Protokol 7T Pompe_TC 2
Recruitment arrangements (for publication) Recruitment 1
Subject information and informed consent form (for publication) Participant information 4
Subject information and informed consent form (for publication) Participant information_TC 1
Summary of Product Characteristics (SmPC) (for publication) Blank 1
Synopsis of the protocol (for publication) Synopsis 7T Pompe 2
Synopsis of the protocol (for publication) Synopsis 7T Pompe_TC 2

Application history

2 submissions — initial application plus substantial / non-substantial modifications

#TypeCodeSubmittedReference MSConclusionDecision date
1 INITIAL IN 2023-11-14 Denmark Acceptable
2024-01-11
2024-01-16
2 SUBSTANTIAL MODIFICATION SM-1 2025-06-16 Denmark Acceptable
2025-08-22
2025-08-22